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FREM2

Domain

The Calx-beta domains bind calcium with high affinity and undergo a major conformational shift upon binding.

Function

Extracellular matrix protein required for maintenance of the integrity of the skin epithelium and for maintenance of renal epithelia (PubMed:15838507). Required for epidermal adhesion (PubMed:15838507). Involved in the development of eyelids and the anterior segment of the eyeballs (PubMed:29688405, PubMed:30802441).

Involvement in disease

Fraser syndrome 2

FRASRS2

A form of Fraser syndrome, an autosomal recessive disorder characterized by cryptophthalmos, cutaneous syndactyly, and urogenital abnormalities including renal agenesis or hypoplasia. Additional features include abnormalities of the larynx, ear malformations, and facial abnormalities.

None

The disease is caused by variants affecting the gene represented in this entry.

Cryptophthalmos, unilateral or bilateral, isolated

CRYPTOP

An autosomal dominant, rare condition characterized by congenital eyelid malformation with an underlying malformed eye. It can be bilateral or unilateral and is classified into complete (typical), incomplete (atypical) and abortive (congenital symblepharon) forms. The skin of patients with complete cryptophthalmos extends uninterrupted from the forehead to the cheek, whereas incomplete cryptophthalmos exists when there is medial eyelid fusion, but coincident intact lateral structures. The symblepharon variety presents with fusion of the upper eyelid skin to the superior aspect of the globe. The complete variety is the most common form.

None

The disease is caused by variants affecting the gene represented in this entry.

Sequence similarities

Belongs to the FRAS1 family.

Cellular localization

  • Cell membrane
  • Single-pass type I membrane protein

Alternative names

  • FRAS1-related extracellular matrix protein 2
  • ECM3 homolog
  • FREM2

Target type

Proteins

Molecular weight

351157Da