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TRMT10A

Function

S-adenosyl-L-methionine-dependent guanine N(1)-methyltransferase that catalyzes the formation of N(1)-methylguanine at position 9 (m1G9) in tRNAs (PubMed:23042678, PubMed:25053765). Probably not able to catalyze formation of N(1)-methyladenine at position 9 (m1A9) in tRNAs (PubMed:23042678).

Involvement in disease

Microcephaly, short stature, and impaired glucose metabolism 1

MSSGM1

An autosomal recessive disease characterized by microcephaly, intellectual disability, short stature, and disturbed glucose metabolism. Additional clinical features include delayed puberty, hypoglycemia-related seizures, hyperinsulinemic hypoglycemia, and early-onset diabetes.

None

The disease is caused by variants affecting the gene represented in this entry.

Sequence Similarities

Belongs to the class IV-like SAM-binding methyltransferase superfamily. TRM10 family.

Tissue Specificity

Expressed in embryonic and fetal brain. It is expressed throughout the dorsal telencephalon at 8 and 11 weeks of gestation, with highest expression in ventricular zone and marginal zone. Detected in cerebellar cortex and nuclei, but not in dorsal telencephalon, at later stages.

Cellular localization

Alternative names

RG9MTD2, TRMT10A, tRNA methyltransferase 10 homolog A, RNA (guanine-9-)-methyltransferase domain-containing protein 2, tRNA (guanine(9)-N(1))-methyltransferase TRMT10A

swissprot:Q8TBZ6 omim:616013 entrezGene:93587