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Function

Tight junction-associated protein that is involved in the survival of auditory hair cells and hearing. Maybe by modulating the barrier properties and mechanical stability of tight junctions. Has no peptidase activity (PubMed:14715245).

Involvement in disease

Cholestasis, progressive familial intrahepatic, 7, with or without hearing loss

PFIC7

An autosomal recessive form of progressive cholestasis, a disorder characterized by early onset of cholestasis that progresses to hepatic fibrosis, cirrhosis, and end-stage liver disease. Some PFIC7 patients develop hearing loss in childhood.

None

The disease is caused by variants affecting the gene represented in this entry.

Sequence similarities

Belongs to the peptidase C19 family.

Tissue specificity

Expressed predominantly in skeletal muscle and heart.

Cellular localization

  • Cell junction
  • Tight junction

Alternative names

KIAA1350, USP53, Inactive ubiquitin carboxyl-terminal hydrolase 53, Inactive ubiquitin-specific peptidase 53

Target type

Proteins

Molecular weight

120806Da

We found 1 product in 1 category

Proteins & Peptides

Target

Species of origin

Search our catalogue for 'USP53' (1)

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